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joubert_syndrome [2025/11/02 23:21] – [Eye Findings] Scott Larsonjoubert_syndrome [2025/11/02 23:26] (current) – [Etiology] Scott Larson
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     * Nystagmus – pendular, rotary, horizontal, see-saw, torsional     * Nystagmus – pendular, rotary, horizontal, see-saw, torsional
     * Supranuclear Ocular motor palsies     * Supranuclear Ocular motor palsies
-    * Strabismus (80%) +    * Strabismus (up to 80%) 
       * Horizontal (esotropia or exotropia) or vertical        * Horizontal (esotropia or exotropia) or vertical 
   * **Congenital Retinal Dystrophy** (30%)   * **Congenital Retinal Dystrophy** (30%)
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 ==== Etiology ==== ==== Etiology ====
-  * Autosomal Recessive+  * Defects in function of primary cilia, one of the ciliopathies  
 +  * Mostly Autosomal Recessive 
 +    * Half the cases have a mutation in only one of 4 genes: AHI1 15%, C5orf42 13%, KIAA0586 11% and CSPP1 10% 
 +    * at least 28 genes implicated most related to cilia formation/function 
 +    * 
   * First described in 1969, by 1991, 94 patients reported   * First described in 1969, by 1991, 94 patients reported
   * More commonly reported in cultures of consanguinity, although distributed worldwide   * More commonly reported in cultures of consanguinity, although distributed worldwide